Ankyloglossum Superius Syndrome compromising a neonatal airway: Considerations in congenital oral airway obstructions

Jason F. Ohlstein, Pablo L. Padilla, Rachel K. Garza, Brian D. Masel, Amr Abouleish, Harold Pine, Wasyl Szeremeta

Research output: Contribution to journalArticle

Abstract

We report the case of a 37-week old newborn presenting on day 1 of life with an apparent congenital fusion of the tongue to the hard palate, consistent with Ankyloglossum Superius syndrome. Physical exam along with endoscopy showed apparent fusion of the floor of the mouth to the anterior hard palate displacing the tongue into the nasal cavity and obstructing the oral airway. The child was nasotracheally intubated and brought to the operating room for lysis of the fusion under binocular microscopy. We review the literature on this rare condition and provide an algorithm for evaluating the neonatal airway in the setting of congenital oral abnormalities.

LanguageEnglish (US)
Pages167-170
Number of pages4
JournalInternational Journal of Pediatric Otorhinolaryngology
Volume117
DOIs
StatePublished - Feb 1 2019

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Hard Palate
Airway Obstruction
Mouth Abnormalities
Tongue
Mouth Floor
Nasal Cavity
Operating Rooms
Endoscopy
Microscopy
Newborn Infant

Keywords

  • Ankyloglossum Superius Syndrome
  • Congenital oral anomalies
  • Neonatal airway management
  • Tongue tie

ASJC Scopus subject areas

  • Pediatrics, Perinatology, and Child Health
  • Otorhinolaryngology

Cite this

Ankyloglossum Superius Syndrome compromising a neonatal airway : Considerations in congenital oral airway obstructions. / Ohlstein, Jason F.; Padilla, Pablo L.; Garza, Rachel K.; Masel, Brian D.; Abouleish, Amr; Pine, Harold; Szeremeta, Wasyl.

In: International Journal of Pediatric Otorhinolaryngology, Vol. 117, 01.02.2019, p. 167-170.

Research output: Contribution to journalArticle

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